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Research ResourceDRUG DEVELOPMENT
Hyperactive locomotion in a Drosophila model is a functional readout for the synaptic abnormalities underlying fragile X syndrome
- View ORCID ProfileRisa Kashima1,*,
- View ORCID ProfilePatrick L. Redmond1,*,
- Prajakta Ghatpande1,
- View ORCID ProfileSougata Roy2,
- View ORCID ProfileThomas B. Kornberg1,
- View ORCID ProfileThomas Hanke3,
- View ORCID ProfileStefan Knapp3,4,
- View ORCID ProfileGiorgio Lagna1, and
- View ORCID ProfileAkiko Hata1,†
- 1Cardiovascular Research Institute, University of California, San Francisco, San Francisco, CA 94158, USA.
- 2Department of Cell Biology and Molecular Genetics, University of Maryland, College Park, MD 20742, USA.
- 3Institute of Pharmaceutical Chemistry and Buchmann Institute for Life Sciences, Goethe University, Frankfurt, Germany.
- 4Department of Clinical Medicine, Structural Genomics Consortium, University of Oxford, Oxford OX3 7DQ, U.K.
- ↵†Corresponding author. Email: akiko.hata{at}ucsf.edu
↵* These authors contributed equally to this work.
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Science Signaling 02 May 2017:
Vol. 10, Issue 477, eaai8133
DOI: 10.1126/scisignal.aai8133
Vol. 10, Issue 477, eaai8133
DOI: 10.1126/scisignal.aai8133
Risa Kashima
1Cardiovascular Research Institute, University of California, San Francisco, San Francisco, CA 94158, USA.
Patrick L. Redmond
1Cardiovascular Research Institute, University of California, San Francisco, San Francisco, CA 94158, USA.
Prajakta Ghatpande
1Cardiovascular Research Institute, University of California, San Francisco, San Francisco, CA 94158, USA.
Sougata Roy
2Department of Cell Biology and Molecular Genetics, University of Maryland, College Park, MD 20742, USA.
Thomas B. Kornberg
1Cardiovascular Research Institute, University of California, San Francisco, San Francisco, CA 94158, USA.
Thomas Hanke
3Institute of Pharmaceutical Chemistry and Buchmann Institute for Life Sciences, Goethe University, Frankfurt, Germany.
Stefan Knapp
3Institute of Pharmaceutical Chemistry and Buchmann Institute for Life Sciences, Goethe University, Frankfurt, Germany.
4Department of Clinical Medicine, Structural Genomics Consortium, University of Oxford, Oxford OX3 7DQ, U.K.
Giorgio Lagna
1Cardiovascular Research Institute, University of California, San Francisco, San Francisco, CA 94158, USA.
Akiko Hata
1Cardiovascular Research Institute, University of California, San Francisco, San Francisco, CA 94158, USA.
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